Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication

Introduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult w...

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Autores principales: Mathieu Chamberland, Marc-Antoine Poulin, Danielle Beaudoin
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Publicado: Hindawi Limited 2021
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spelling oai:doaj.org-article:7bd1e22ab22440a790c9e9d717f4fdf92021-11-29T00:55:40ZBilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication2090-677310.1155/2021/1315117https://doaj.org/article/7bd1e22ab22440a790c9e9d717f4fdf92021-01-01T00:00:00Zhttp://dx.doi.org/10.1155/2021/1315117https://doaj.org/toc/2090-6773Introduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult white male affected by this syndrome underwent an uneventful total thyroidectomy for malignancy and suffered delayed bilateral recurrent laryngeal nerve palsy in the early postoperative hours. The palsy spontaneously resolved after a five-week course. Conclusion. Given the rarity of this severe condition and the absence of surgical or medical causes identifiable, there is possibility that it is the neurological involvement caused by TAS that predisposed the patient to this adverse outcome, precipitated by standard manipulations during surgery.Mathieu ChamberlandMarc-Antoine PoulinDanielle BeaudoinHindawi LimitedarticleOtorhinolaryngologyRF1-547ENCase Reports in Otolaryngology, Vol 2021 (2021)
institution DOAJ
collection DOAJ
language EN
topic Otorhinolaryngology
RF1-547
spellingShingle Otorhinolaryngology
RF1-547
Mathieu Chamberland
Marc-Antoine Poulin
Danielle Beaudoin
Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
description Introduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult white male affected by this syndrome underwent an uneventful total thyroidectomy for malignancy and suffered delayed bilateral recurrent laryngeal nerve palsy in the early postoperative hours. The palsy spontaneously resolved after a five-week course. Conclusion. Given the rarity of this severe condition and the absence of surgical or medical causes identifiable, there is possibility that it is the neurological involvement caused by TAS that predisposed the patient to this adverse outcome, precipitated by standard manipulations during surgery.
format article
author Mathieu Chamberland
Marc-Antoine Poulin
Danielle Beaudoin
author_facet Mathieu Chamberland
Marc-Antoine Poulin
Danielle Beaudoin
author_sort Mathieu Chamberland
title Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
title_short Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
title_full Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
title_fullStr Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
title_full_unstemmed Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
title_sort bilateral recurrent laryngeal nerve palsy following total thyroidectomy in triple a syndrome, an unexpected but critical complication
publisher Hindawi Limited
publishDate 2021
url https://doaj.org/article/7bd1e22ab22440a790c9e9d717f4fdf9
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AT marcantoinepoulin bilateralrecurrentlaryngealnervepalsyfollowingtotalthyroidectomyintripleasyndromeanunexpectedbutcriticalcomplication
AT daniellebeaudoin bilateralrecurrentlaryngealnervepalsyfollowingtotalthyroidectomyintripleasyndromeanunexpectedbutcriticalcomplication
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